Statistical adjustment of genotyping error in a case-control study of childhood leukaemia.

Background: Genotyping has become more cost-effective and less invasive with the use of buccal cell sampling. However, low or fragmented DNA yields from buccal cells collected using FTA cards often requires additional whole genome amplification to produce sufficient DNA for genotyping. In our case-c...

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Published in:BMC Medical Research Methodology Vol. 12; no. 1; pp. 141 - 142
Main Authors: Cooper, Matthew N, de Klerk, Nicholas H, Greenop, Kathryn R, Jamieson, Sarra E, Anderson, Denise, van Bockxmeer, Frank M, Armstrong, Bruce K, Milne, Elizabeth
Format: research Journal Article
Published: BioMed Central 2012
Online Access:View this record in EBSCOhost
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        10.1186/1471-2288-12-141
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        atl: Statistical adjustment of genotyping error in a case-control study of childhood leukaemia.
      aug:
        au:
          Cooper, Matthew N
          de Klerk, Nicholas H
          Greenop, Kathryn R
          Jamieson, Sarra E
          Anderson, Denise
          van Bockxmeer, Frank M
          Armstrong, Bruce K
          Milne, Elizabeth
        affil: Telethon Institute for Child Health Research, Centre for Child Health Research, University of Western Australia, P,O, Box 855, West Perth, 6872, WA, Australia. mcooper@ichr.uwa.edu.au.
      sug:
        subj:
          DNA
          Leukemia Diagnosis
          Case Control Studies
          Child
          DNA Fingerprinting Methods
          Diagnostic Errors
          Female
          Genetics
          Genetic Techniques
          Human
          Leukemia
          Male
          Reagent Kits, Diagnostic
          Child: 6-12 years
          Female
          Male
      ab: Background: Genotyping has become more cost-effective and less invasive with the use of buccal cell sampling. However, low or fragmented DNA yields from buccal cells collected using FTA cards often requires additional whole genome amplification to produce sufficient DNA for genotyping. In our case-control study of childhood leukaemia, discordance was found between genotypes derived from blood and whole genome amplified FTA buccal DNA samples. We aimed to develop a user-friendly method to correct for this genotype misclassification, as existing methods were not suitable for use in our study.Methods: Discordance between the results of blood and buccal-derived DNA was assessed in childhood leukaemia cases who had both blood and FTA buccal samples. A method based on applying misclassification probabilities to measured data and combining results using multiple imputations, was devised to correct for error in the genotypes of control subjects, for whom only buccal samples were available, to minimize bias in the odds ratios in the case-control analysis.Results: Application of the correction method to synthetic datasets showed it was effective in producing correct odds ratios from data with known misclassification. Moreover, when applied to each of six bi-allelic loci, correction altered the odds ratios in the logically anticipated manner given the degree and direction of the misclassification revealed by the investigations in cases. The precision of the effect estimates decreased with decreasing size of the misclassification data set.Conclusions: Bias arising from differential genotype misclassification can be reduced by correcting results using this method whenever data on concordance of genotyping results with those from a different and probably better DNA source are available.
      pubtype: Academic Journal
      doctype:
        research
        Journal Article
      ougenre: Article
    language: English
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