Novel CSF biomarkers for frontotemporal lobar degenerations.

Objective: To identify antemortem CSF diagnostic biomarkers that can potentially distinguish between the 2 main causes of frontotemporal lobar degeneration (FTLD), i.e., FTLD with TDP-43 pathology (FTLD-TDP) and FTLD with tau pathology (FTLD-tau).Methods: CSF samples were collected antemortem from 2...

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Publicado en:Neurology Vol. 75; no. 23; pp. 2079 - 2087
Autores principales: Hu WT, Chen-Plotkin A, Grossman M, Arnold SE, Clark CM, Shaw LM, McCluskey L, Elman L, Hurtig HI, Siderowf A, Lee VM, Soares H, Trojanowski JQ, Hu, W T, Chen-Plotkin, A, Grossman, M, Arnold, S E, Clark, C M, Shaw, L M, McCluskey, L
Formato: research Journal Article
Publicado: Lippincott Williams & Wilkins 12/7/2010
Acceso en línea:Ver este registro en EBSCOhost
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      dt: 12/7/2010
      vid: 75
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      pub: Lippincott Williams & Wilkins
      place: Baltimore, Maryland
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        10.1212/WNL.0b013e318200d78d
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      formats:
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        atl: Novel CSF biomarkers for frontotemporal lobar degenerations.
      aug:
        au:
          Hu WT
          Chen-Plotkin A
          Grossman M
          Arnold SE
          Clark CM
          Shaw LM
          McCluskey L
          Elman L
          Hurtig HI
          Siderowf A
          Lee VM
          Soares H
          Trojanowski JQ
          Hu, W T
          Chen-Plotkin, A
          Grossman, M
          Arnold, S E
          Clark, C M
          Shaw, L M
          McCluskey, L
        affil: Department of Neurology, University of Pennsylvania School of Medicine, Philadelphia 19104-4283, USA
      sug:
        subj:
          Biological Markers Cerebrospinal Fluid
          Proteins Metabolism
          Dementia Cerebrospinal Fluid
          Neurodegenerative Diseases Cerebrospinal Fluid
          Adrenocorticotropic Hormone Cerebrospinal Fluid
          Aged
          Alzheimer's Disease Cerebrospinal Fluid
          Prospective Studies
          Female
          Dementia Complications
          Human
          Interleukins Cerebrospinal Fluid
          Male
          Psychological Tests
          Middle Age
          Neuropsychological Tests
          Nonparametric Statistics
          Neurodegenerative Diseases Complications
          Aged: 65+ years
          Middle Aged: 45-64 years
          Female
          Male
      ab: Objective: To identify antemortem CSF diagnostic biomarkers that can potentially distinguish between the 2 main causes of frontotemporal lobar degeneration (FTLD), i.e., FTLD with TDP-43 pathology (FTLD-TDP) and FTLD with tau pathology (FTLD-tau).Methods: CSF samples were collected antemortem from 23 patients with FTLD with known pathology to form a autopsy cohort as part of a comparative biomarker study that additionally included 33 living cognitively normal subjects and 66 patients with autopsy-confirmed Alzheimer disease (AD). CSF samples were also collected from 80 living patients clinically diagnosed with frontotemporal dementia (FTD). Levels of 151 novel analytes were measured via a targeted multiplex panel enriched in neuropeptides, cytokines, and growth factors, along with levels of CSF biomarkers for AD.Results: CSF levels of multiple analytes differed between FTLD-TDP and FTLD-tau, including Fas, neuropeptides (agouti-related peptide and adrenocorticotropic hormone), and chemokines (IL-23, IL-17). Classification by random forest analysis achieved high sensitivity for FTLD-TDP (86%) with modest specificity (78%) in the autopsy cohort. When the classification algorithm was applied to a living FTD cohort, semantic dementia was the phenotype with the highest predicted proportion of FTLD-TDP. When living patients with behavioral variant FTD were examined in detail, those predicted to have FTLD-TDP demonstrated neuropsychological differences vs those predicted to have FTLD-tau in a pattern consistent with previously reported trends in autopsy-confirmed cases.Conclusions: Clinical cases with FTLD-TDP and FTLD-tau pathology can be potentially identified antemortem by assaying levels of specific analytes that are well-known and readily measurable in CSF.
      pubtype: Academic Journal
      doctype:
        research
        Journal Article
      ougenre: Article
    language: English
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