Thickening of the cauda equina roots: a common finding in Krabbe disease.

Objectives: Evaluation of Krabbe disease burden and eligibility for hematopoietic stem cell transplantation are often based on neuroimaging findings using the modified Loes scoring system, which encompasses central but not peripheral nervous system changes. We show that quantitative evaluation of th...

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Publicado en:European Radiology Vol. 26; no. 10; pp. 3377 - 3383
Autores principales: Hwang, Misun, Zuccoli, Giulio, Panigrahy, Ashok, Rodriguez, David, Poe, Michele, Escolar, Maria, Poe, Michele D, Escolar, Maria L
Formato: research Journal Article
Publicado: Springer Nature Oct2016
Acceso en línea:Ver este registro en EBSCOhost
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      dt: Oct2016
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      pub: Springer Nature
      place: New York, New York
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        atl: Thickening of the cauda equina roots: a common finding in Krabbe disease.
      aug:
        au:
          Hwang, Misun
          Zuccoli, Giulio
          Panigrahy, Ashok
          Rodriguez, David
          Poe, Michele
          Escolar, Maria
          Poe, Michele D
          Escolar, Maria L
        affil: Department of Radiology of University of Pittsburgh Medical Center , 3950 Presby South Tower Pittsburgh 15213 USA
      sug:
        subj:
          Cauda Equina Pathology
          Leukodystrophy, Globoid Cell Pathology
          Male
          Leukodystrophy, Globoid Cell
          Infant
          Human
          Lumbar Vertebrae
          Cauda Equina
          Child, Preschool
          Magnetic Resonance Imaging Methods
          Retrospective Design
          Female
          Validation Studies
          Comparative Studies
          Evaluation Research
          Multicenter Studies
          Infant: 1-23 months
          Child, Preschool: 2-5 years
          Male
          Female
      ab: Objectives: Evaluation of Krabbe disease burden and eligibility for hematopoietic stem cell transplantation are often based on neuroimaging findings using the modified Loes scoring system, which encompasses central but not peripheral nervous system changes. We show that quantitative evaluation of thickened cauda equina nerve roots may improve the evaluation of Krabbe disease and therapeutic guidance.Methods: Lumbar spine MRI scans of patients obtained between March 2013 and September 2013 were retrospectively evaluated and compared to those of controls. Quantitative evaluation of cauda equina roots was performed on the axial plane obtained approximately 5 mm below the conus medullaris. The largest nerves in the right and left anterior quadrants of the spinal canal were acquired.Results: Fifteen symptomatic patients with Krabbe disease (5-44 months old) and eleven age-matched controls were evaluated. The average areas (mm(2)) of anterior right and left nerves were 1.40 and 1.23, respectively, for patients and 0.61 and 0.60 for controls (differences: 0.79 and 0.63; p < 0.001).Conclusions: Cauda equina nerve root thickening is associated with Krabbe disease in both treated and untreated patients. Adding lumbar spine MRI to the current neurodiagnostic protocols, which fails to account for peripheral nerve abnormalities, will likely facilitate the diagnosis of Krabbe disease.Key Points: • Neuroimaging is valuable for evaluating cauda equina nerve abnormality in Krabbe disease • MRI can be used to quantitatively evaluate cauda equina nerve thickening • Lumbar MRI could be useful for diagnosis and treatment monitoring of Krabbe disease.
      pubtype: Academic Journal
      doctype:
        research
        Journal Article
      ougenre: Article
    language: English
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