Imaging findings of Copa syndrome in a 12-year-old boy.

Copa syndrome is a newly described autosomal dominant autoinflammatory disease that presents as pulmonary hemosiderosis and polyarticular arthritis. Twenty-one cases from five families have been reported to date. We present chest computed tomography (CT) and temporomandibular joint magnetic resonanc...

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Publicado en:Pediatric Radiology Vol. 48; no. 2; pp. 279 - 283
Autores principales: Noorelahi, Razan, Perez, Geovany, Otero, Hansel J.
Formato: case study Journal Article
Publicado: Springer Nature Feb2018
Acceso en línea:Ver este registro en EBSCOhost
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      pub: Springer Nature
      place: New York, New York
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        atl: Imaging findings of Copa syndrome in a 12-year-old boy.
      aug:
        au:
          Noorelahi, Razan
          Perez, Geovany
          Otero, Hansel J.
        affil: Department of Diagnostic Imaging and Radiology, Children’s National Health System, The George Washington University School of Medicine & Health Services, 111 Michigan Ave. NW, 20010, Washington, DC, USA
      sug:
        subj:
          Immunologic Deficiency Syndromes
          Hemosiderosis
          Arthritis
          Lung Diseases
          Magnetic Resonance Imaging
          Tomography, X-Ray Computed
          Temporomandibular Joint Diseases
          Immunologic Deficiency Syndromes Drug Therapy
          Hemosiderosis Drug Therapy
          Male
          Child
          Mutation
          Contrast Media
          Respiratory Function Tests
          Temporomandibular Joint Diseases Drug Therapy
          Diagnosis, Differential
          Arthritis Drug Therapy
          Lung Diseases Drug Therapy
          Arthritis Impact Measurement Scales
          Child: 6-12 years
          Male
      ab: Copa syndrome is a newly described autosomal dominant autoinflammatory disease that presents as pulmonary hemosiderosis and polyarticular arthritis. Twenty-one cases from five families have been reported to date. We present chest computed tomography (CT) and temporomandibular joint magnetic resonance (MR) findings of a 12-year-old boy presenting with dyspnea on exertion, fatigue and clubbing. Additional findings included a restrictive pattern of pulmonary involvement and positive inflammatory markers and autoantibodies. Genetic testing revealed a p.W240R variant of the COPA gene confirming the diagnosis of Copa syndrome. CT of the chest showed a nonspecific interstitial pneumonia pattern distributed mainly in the lower lobes. MR of the temporomandibular joints and follow-up CT three years later are also described.
      pubtype: Academic Journal
      doctype:
        case study
        Journal Article
      ougenre: Article
    language: English
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