Evaluating growth failure with diffusion tensor imaging in pediatric survivors of high-risk neuroblastoma treated with high-dose cis-retinoic acid.

Background: The survival of patients with high-risk neuroblastoma has increased with multimodal therapy, but most survivors demonstrate growth failure.Objective: To assess physeal abnormalities in children with high-risk neuroblastoma in comparison to normal controls by using diffusion tensor imagin...

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Publicado en:Pediatric Radiology Vol. 49; no. 8; pp. 1056 - 1066
Autores principales: Delgado, Jorge, Jaramillo, Diego, Chauvin, Nancy A., Guo, Michelle, Stratton, Mackenzie S., Sweeney, Hannah E., Barrera, Christian A., Mostoufi-Moab, Sogol
Formato: Journal Article
Publicado: Springer Nature Jul2019
Acceso en línea:Ver este registro en EBSCOhost
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      dt: Jul2019
      vid: 49
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      pub: Springer Nature
      place: New York, New York
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        10.1007/s00247-019-04409-1
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        atl: Evaluating growth failure with diffusion tensor imaging in pediatric survivors of high-risk neuroblastoma treated with high-dose cis-retinoic acid.
      aug:
        au:
          Delgado, Jorge
          Jaramillo, Diego
          Chauvin, Nancy A.
          Guo, Michelle
          Stratton, Mackenzie S.
          Sweeney, Hannah E.
          Barrera, Christian A.
          Mostoufi-Moab, Sogol
        affil: Department of Radiology, Massachusetts General Hospital, Boston, MA, USA
      sug:
        subj:
          Tretinoin Therapeutic Use
          Neuroblastoma
          Magnetic Resonance Imaging Methods
          Growth Disorders Drug Therapy
          Neuroblastoma Drug Therapy
          Retrospective Design
          Sex Factors
          Risk Assessment
          Growth Disorders Etiology
          Female
          Tretinoin Adverse Effects
          Body Height Drug Effects
          Dose-Response Relationship, Drug
          Adolescence
          Femur
          Age Factors
          Neuroblastoma Mortality
          Child
          Multivariate Analysis
          Drug Administration Schedule
          Case Control Studies
          Survivors
          Male
          Femur Pathology
          Linear Regression
          Checklists
          Short Portable Mental Status Questionnaire
          Adolescent: 13-18 years
          Child: 6-12 years
          Female
          Male
      ab: Background: The survival of patients with high-risk neuroblastoma has increased with multimodal therapy, but most survivors demonstrate growth failure.Objective: To assess physeal abnormalities in children with high-risk neuroblastoma in comparison to normal controls by using diffusion tensor imaging (DTI) of the distal femoral physis and adjacent metaphysis.Materials and Methods: We prospectively obtained physeal DTI at 3.0 T in 20 subjects (mean age: 12.4 years, 7 females) with high-risk neuroblastoma treated with high-dose cis-retinoic acid, and 20 age- and gender-matched controls. We compared fractional anisotropy (FA), normalized tract volume (cm3/cm2) and tract concentration (tracts/cm2) between the groups, in relation to height Z-score and response to growth hormone therapy. Tractography images were evaluated qualitatively.Results: DTI parameters were significantly lower in high-risk neuroblastoma survivors compared to controls (P<0.01), particularly if the patients were exposed to both cis-retinoic acid and total body irradiation (P<0.05). For survivors and controls, DTI values were respectively [mean ± standard deviation]: tract concentration (tracts/cm2), 23.2±14.7 and 36.7±10.5; normalized tract volume (cm3/cm2), 0.44±0.27 and 0.70±0.21, and FA, 0.22±0.05 and 0.26±0.02. High-risk neuroblastoma survivors responding to growth hormone compared to non-responders had higher FA (0.25±0.04 and 0.18±0.03, respectively, P=0.02), and tract concentration (tracts/cm2) (31.4±13.7 and 14.8±7.9, respectively, P<0.05). FA, normalized tract volume and tract concentration were linearly related to height Z-score (R2>0.31; P<0.001). Qualitatively, tracts were nearly absent in all non-responders to growth hormone and abundant in all responders (P=0.02).Conclusion: DTI shows physeal abnormalities that correlate with short stature in high-risk neuroblastoma survivors and demonstrates response to growth hormone treatment.
      pubtype: Academic Journal
      doctype: Journal Article
      ougenre: Article
    language: English
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