A Novel PAX6 Mutation in a Patient with Nonsyndromic Dominant Foveal Hypoplasia and Congenital Nystagmus.

Background: Foveal hypoplasia is a disorder in which the fovea does not develop normally. It is commonly associated with congenital nystagmus and other developmental conditions, such as aniridia and albinism. Case Report: We examined a 15-year-old female who presented with foveal hypoplasia and cong...

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Detalles Bibliográficos
Publicado en:Optometry & Visual Performance Vol. 7; no. 5/6; pp. 323 - 327
Autores principales: Vezinaw, Chloe M., Fishman, Gerald A., John Chiang
Formato: case study diagnostic images pictorial tables/charts Journal Article
Publicado: Optometric Extension Program Dec2019
Acceso en línea:Ver este registro en EBSCOhost
Descripción
Sumario:Background: Foveal hypoplasia is a disorder in which the fovea does not develop normally. It is commonly associated with congenital nystagmus and other developmental conditions, such as aniridia and albinism. Case Report: We examined a 15-year-old female who presented with foveal hypoplasia and congenital nystagmus in the absence of any systemic or anterior segment abnormalities. Genetic testing showed a novel PAX6 missense mutation. Conclusion: This report highlights a case of autosomal dominant, isolated foveal hypoplasia with a novel PAX6 mutation without any anterior segment anomalies.