Baseline characteristics and long-term outcomes of steroid-resistant nephrotic syndrome in children: impact of initial kidney histology.

Background: Although many pediatric nephrologists consider focal segmental glomerulosclerosis (FSGS) and minimal change disease (MCD) as separate clinical entities, whether the initial histology could affect clinical courses in children with steroid-resistant nephrotic syndrome (SRNS) suspected of h...

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Published in:Pediatric Nephrology Vol. 35; no. 12; pp. 2377 - 2382
Main Authors: Watanabe, Yoshitaka, Fujinaga, Shuichiro, Endo, Amane, Endo, Shota, Nakagawa, Mayu, Sakuraya, Koji
Format: research tables/charts Journal Article
Published: Springer Nature Dec2020
Online Access:View this record in EBSCOhost
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      dt: Dec2020
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      pub: Springer Nature
      place: New York, New York
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        10.1007/s00467-020-04760-8
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        atl: Baseline characteristics and long-term outcomes of steroid-resistant nephrotic syndrome in children: impact of initial kidney histology.
      aug:
        au:
          Watanabe, Yoshitaka
          Fujinaga, Shuichiro
          Endo, Amane
          Endo, Shota
          Nakagawa, Mayu
          Sakuraya, Koji
        affil: Division of Nephrology, Saitama Children's Medical Center, 1-2 Shintoshin, Chuo-ku, 330-8777, Saitama-city Saitama, Japan
      sug:
        subj:
          Steroids
          Drug Resistance
          Nephrotic Syndrome Prognosis
          Nephrotic Syndrome Diagnosis
          Nephrotic Syndrome Pathology
          Disease Attributes
          Human
          Retrospective Design
          Prospective Studies
          Descriptive Statistics
          Kidney Failure, Acute Epidemiology
          Proteinuria Epidemiology
          Incidence
          Comparative Studies
          Glomerulosclerosis, Focal Segmental
          Nephrosis
          Disease Remission
          Time Factors
          Biopsy
          Infant
          Child, Preschool
          Child
          Nephrotic Syndrome Etiology
          Nephrotic Syndrome Immunology
          Nephrotic Syndrome Drug Therapy
          Age of Onset
          Immunosuppressive Agents Therapeutic Use
          Nephrotic Syndrome Symptoms
          Infant: 1-23 months
          Child, Preschool: 2-5 years
          Child: 6-12 years
      ab: Background: Although many pediatric nephrologists consider focal segmental glomerulosclerosis (FSGS) and minimal change disease (MCD) as separate clinical entities, whether the initial histology could affect clinical courses in children with steroid-resistant nephrotic syndrome (SRNS) suspected of having an immune-based etiology remains unknown, especially for long-term outcomes. Methods: We retrospectively reviewed long-term outcomes (> 3 years; median follow-up, 9.1 years) of 21 children with initial SRNS (FSGS, N = 9; MCD, N = 12) who achieved complete remission with immunosuppressive agents, including cyclosporine. Results: At NS onset, incidence of acute kidney injury (67% vs. 8%, P < 0.05) and proportion of patients with non-selective proteinuria (56% vs. 0%, P < 0.01) were significantly higher in the FSGS group than the MCD group. Furthermore, median days until complete remission after treatment was significantly longer in the FSGS group than the MCD group (116 days vs. 45 days, P < 0.001). Although subsequent biopsy histology of the 12 patients in the MCD group was still identical in all MCD, three of nine patients in the FSGS group were reclassified from FSGS to MCD at second biopsy. At last visit, all patients maintained complete remission, and none developed chronic kidney disease. Conclusions: Initial presentation in the FSGS group was characterized by more severe clinical manifestations than the MCD group. If complete remission is achieved, FSGS and MCD in children with immune-mediated SRNS may constitute a single disease spectrum because the long-term outcomes are favorable, irrespective of initial histology.
      pubtype: Academic Journal
      doctype:
        research
        tables/charts
        Journal Article
      ougenre: Article
    language: English
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