Analysis of Cytogenetic Abnormalities in Iranian Patients with Syndromic Autism Spectrum Disorder: A Case Series.

Objective Autism spectrum disorder (ASD) is a heterogeneous neuropsychiatric group of pervasive developmental disorders mainly diagnosed through the complex behavioral phenotype. According to strong genetic involvement, detecting the chromosome regions and the key genes linked to autism can help to...

Descripción completa

Detalles Bibliográficos
Publicado en:Iranian Journal of Child Neurology Vol. 16; no. 2; pp. 117 - 129
Autores principales: GHASEMI, Mohammad Reza, ZARGARI, Peyman, SADEGHI, Hossein, BAGHERI, Saman, SADEGHI, Behnia, MIRFAKHRAIE, Reza, EKRAMI, Mahdis, MOHAMMADI SARVALEH, Sepideh, HASHEMI GORJI, Farzad, RAZJOUYAN, Katayoon, OMRANI, Davood, KIM, Hyung goo, MIRYOUNESI, Mohammad
Formato: pictorial research tables/charts Journal Article
Publicado: Iranian Journal of Child Neurology Spring2022
Acceso en línea:Ver este registro en EBSCOhost
fields @attributes:
  recordID: 1
pdfLink:
plink: https://search.ebscohost.com/login.aspx?direct=true&db=ccm&AN=156309909&site=ehost-live
header:
  @attributes:
    shortDbName: ccm
    uiTerm: 156309909
    longDbName: CINAHL Complete
    uiTag: AN
  controlInfo:
    bkinfo:
    dissinfo:
    jinfo:
      jid:
        17354668
        A91T
      jtl: Iranian Journal of Child Neurology
      issn: 17354668
      maglogo: N
    pubinfo:
      dt: Spring2022
      vid: 16
      iid: 2
      pid: 56766
      pub: Iranian Journal of Child Neurology
      place: Tehran, <Blank>
    artinfo:
      ui:
        156309909
        156309909
        156309909
        10.22037/ijcn.v16i4.34843
        156309909
      ppf: 117
      ppct: 12
      formats:
        fmt:
          @attributes:
            type: P
      tig:
        atl: Analysis of Cytogenetic Abnormalities in Iranian Patients with Syndromic Autism Spectrum Disorder: A Case Series.
      aug:
        au:
          GHASEMI, Mohammad Reza
          ZARGARI, Peyman
          SADEGHI, Hossein
          BAGHERI, Saman
          SADEGHI, Behnia
          MIRFAKHRAIE, Reza
          EKRAMI, Mahdis
          MOHAMMADI SARVALEH, Sepideh
          HASHEMI GORJI, Farzad
          RAZJOUYAN, Katayoon
          OMRANI, Davood
          KIM, Hyung goo
          MIRYOUNESI, Mohammad
        affil: Department of Medical Genetics, Faculty of Medicine, Shahid Beheshti University of Medical Sciences, Tehran, Iran
      sug:
        subj:
          Autism Spectrum Disorder Iran
          Cytogenetic Analysis
          Human
          Iran
      ab: Objective Autism spectrum disorder (ASD) is a heterogeneous neuropsychiatric group of pervasive developmental disorders mainly diagnosed through the complex behavioral phenotype. According to strong genetic involvement, detecting the chromosome regions and the key genes linked to autism can help to elucidate its etiology. The present study aimed to investigate the value of cytogenetic analysis in syndromic autism and find an association between autism and chromosome abnormalities. Materials & Methods Thirty-six autistic patients from 30 families were recruited, clinically diagnosed with the Diagnostic and Statistical Manual of Mental Disorders (5th ed.; DSM-5). The syndromic patients with additional clinical features (including development delay, attention deficit, hyperactivity disorder, seizure, and language and intellectual impairment) were selected due to elevating the detection rate. Cytogenetics analysis was performed using GTG banding on the patients' cultured fibroblasts. Moreover, array-comparative genomic hybridization (CGH) was also performed for patients with a de novo and novel variant. Results Karyotype analysis in 36 syndromic autistic patients detected chromosomal abnormalities in 2 (5.6%) families, including 46,XY,dup(15)(q11.1q11.2) and 46,XX,ins(7)(q11.1q21.3)dn. In the latter, array-CGH detected 3 abnormalities on chromosome 7, including deletion and insertion on both arms: 46,XX,del(7) (q21.11q21.3),dup(7)(p11.2p14.1p12.3)dn. Conclusion We reported a novel and de novo cytogenetic abnormality on chromosome 7 in an Iranian patient diagnosed with syndromic autism. However, the detection rate in syndromic autism was low, implying that it cannot be utilized as the only diagnostic procedure.
      pubtype: Academic Journal
      doctype:
        pictorial
        research
        tables/charts
        Journal Article
      ougenre: Article
    language: English
    refInfo:
    holdings:
      @attributes:
        islocal: N