ZMIZ1::ABL1 Fusion: An Uncommon Molecular Event With Clinical Implications in Pediatric Cancer.

* Context.--Pediatric B-cell acute lymphoblastic leukemia is genetically and phenotypically heterogeneous, with a genetic landscape including chromosomal translocations that disrupt ABL proto-oncogene 1, non--receptor tyrosine kinase (ABL1). Objective.--To characterize an uncommon chromosomal transl...

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Publicado en:Archives of Pathology & Laboratory Medicine Vol. 149; no. 2; pp. 159 - 165
Autores principales: Booth, Kevin T. A., Schulte, Rachael R., Smith, Laurin, Hongyu Gao, Stohler, Ryan A., Yunlong Liu, Reshmi, Shalini C., Vance, Gail H.
Formato: pictorial research tables/charts Journal Article
Publicado: College of American Pathologists Feb2025
Acceso en línea:Ver este registro en EBSCOhost
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      dt: Feb2025
      vid: 149
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      pub: College of American Pathologists
      place: Northfield, Illinois
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        182777046
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        10.5858/arpa.2024-0082-OA
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        atl: ZMIZ1::ABL1 Fusion: An Uncommon Molecular Event With Clinical Implications in Pediatric Cancer.
      aug:
        au:
          Booth, Kevin T. A.
          Schulte, Rachael R.
          Smith, Laurin
          Hongyu Gao
          Stohler, Ryan A.
          Yunlong Liu
          Reshmi, Shalini C.
          Vance, Gail H.
        affil: Department of Medical and Molecular Genetics, Indiana University School of Medicine, Indianapolis
      sug:
        subj:
          Childhood Neoplasms
          Chromosome Aberrations
          Leukemia, Lymphocytic, Acute Familial and Genetic
          Transcription Factors
          Human
          Genetic Screening
          Karyotyping
          In Situ Hybridization, Fluorescence
          Sequence Analysis
          Models, Structural
          Molecular Structure
          Bone Marrow Examination
      ab: * Context.--Pediatric B-cell acute lymphoblastic leukemia is genetically and phenotypically heterogeneous, with a genetic landscape including chromosomal translocations that disrupt ABL proto-oncogene 1, non--receptor tyrosine kinase (ABL1). Objective.--To characterize an uncommon chromosomal translocation in acute leukemia. Design.--Genetic testing, including karyotype and fluorescence in situ hybridization (FISH) analysis, was used to determine the underlying genetic aberration driving the disorder and to guide disease classification and risk stratification. More-detailed testing using RNA sequencing was performed based on the results from these assays. Threedimensional molecular modeling was used to visualize the impact of aberrant fused transcripts identified by transcriptome profiling. Results.--Karyotype analysis of the bone marrow demonstrated a complex karyotype with, most notably, a t(9;10)(q34.1;q22) translocation. ABL1 break-apart probe FISH findings supported ABL1 disruption. Bone marrow transcriptome analysis revealed mutant ZMIZ1::ABL1 (ZMIZ1, zinc finger MIZ-type containing 1) fusion transcripts as a consequence of t(9;10)(q34.1;q22). Three-dimensional modeling of the mutant ZMIZ1::ABL1 fusion protein confirmed an altered ABL1 protein structure compared to that of the wild type, suggesting a constitutively active conformation. Conclusions.--The t(9;10) translocation resulting in ZMIZ1::ABL1 fusion transcripts is an uncommon form of BCR::ABL1-like (BCR, BCR activator of RhoGEF and GTPase) acute lymphoblastic leukemia. Although the karyotype was complex, identifying the t(9;10)(q34.1; q22) translocation, ABL1 disruption, and ZMIZ1::ABL1 transcript enabled effective ABL1-targeted treatment. Our data support the use of tyrosine kinase inhibitors to treat ZMIZ1::ABL1-derived B-cell acute lymphoblastic leukemia.
      pubtype: Academic Journal
      doctype:
        pictorial
        research
        tables/charts
        Journal Article
      ougenre: Article
    language: English
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