Profiling Autism and Attention Deficit Hyperactivity Disorder Traits in Children with SYNGAP1-Related Intellectual Disability.

SYNGAP1-related ID is a genetic condition characterised by global developmental delay and epilepsy. Individuals with SYNGAP1-related ID also commonly show differences in attention and social communication/interaction and frequently receive additional diagnoses of Autism Spectrum Disorder (ASD) or At...

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Publicado en:Journal of Autism & Developmental Disorders Vol. 55; no. 1; pp. 297 - 310
Autores principales: Wright, Damien, Kenny, Aisling, Mizen, Lindsay A. M., McKechanie, Andrew G., Stanfield, Andrew C.
Formato: research tables/charts Journal Article
Publicado: Springer Nature Jan2025
Acceso en línea:Ver este registro en EBSCOhost
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      pub: Springer Nature
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        atl: Profiling Autism and Attention Deficit Hyperactivity Disorder Traits in Children with SYNGAP1-Related Intellectual Disability.
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          Wright, Damien
          Kenny, Aisling
          Mizen, Lindsay A. M.
          McKechanie, Andrew G.
          Stanfield, Andrew C.
        affil: https://ror.org/01nrxwf90 Patrick Wild Centre, Division of Psychiatry, Kennedy Tower, Royal Edinburgh Hospital, University of Edinburgh, EH10 5HF, Edinburgh, UK
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        subj:
          Genes
          Mutation
          Intellectual Disability Diagnosis
          Autism Spectrum Disorder Familial and Genetic
          Attention Deficit Hyperactivity Disorder Familial and Genetic
          Attention Deficit Hyperactivity Disorder Symptoms
          Social Behavior
          Human
          Funding Source
          Male
          Female
          Child, Preschool
          Child
          Autism Spectrum Disorder Diagnosis
          Attention Deficit Hyperactivity Disorder Diagnosis
          Nervous System Pathology
          Child, Preschool: 2-5 years
          Child: 6-12 years
          Male
          Female
      ab: SYNGAP1-related ID is a genetic condition characterised by global developmental delay and epilepsy. Individuals with SYNGAP1-related ID also commonly show differences in attention and social communication/interaction and frequently receive additional diagnoses of Autism Spectrum Disorder (ASD) or Attention Deficit Hyperactivity Disorder (ADHD). We thus set out to quantify ASD and ADHD symptoms in children with this syndrome. To assess ASD and ADHD, parents and caregivers of a child with SYNGAP1-related ID (N = 34) or a typically developing control (N = 21) completed the Social Responsiveness Scale-2, the Social Communication Questionnaire with a subset of these also completing the Conners-3. We found that those with SYNGAP1-related ID demonstrated higher levels of autistic traits on both the SRS and SCQ than typically developing controls. On the SRS, those with SYNGAP1-related ID scored highest for restricted repetitive behaviours, and were least impaired in social awareness. On the Conners-3, those with SYNGAP1-related ID also showed a high prevalence of ADHD traits, with scores demonstrating difficulties with peer relations but relatively low occurrence of symptoms for DSM-5 conduct disorder and DSM-5 oppositional defiant disorder. Hierarchical clustering analysis highlighted distinct SYNGAP1-related ID subgroups for both ASD and ADHD traits. These findings provide further characterisation of the SYNGAP1-related ID behavioural phenotype, guiding diagnosis, assessment and potential interventions.
      pubtype: Academic Journal
      doctype:
        research
        tables/charts
        Journal Article
      ougenre: Article
    language: English
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