Impact of a Genetic Diagnosis for a Child's Autism on Parental Perceptions.

Genetic testing is recommended as part of an autism assessment, and most parents support genetic testing for their minor children. However, the impact on parents of receiving a monogenetic/ copy number variant diagnosis for autism in their child is not well understood. To explore this, we surveyed a...

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Publicado en:Journal of Autism & Developmental Disorders Vol. 55; no. 5; pp. 1809 - 1824
Autores principales: Wynn, Julia, Karlsen, Anna, Huber, Benjamin, Levine, Alina, Salem, Amanie, White, L. Casey, Luby, Marti, Bezborodko, Ekaterina, Xiao, Sabrina, Chung, Wendy K., Klitzman, Robert L., Appelbaum, Paul S.
Formato: research tables/charts Journal Article
Publicado: Springer Nature May2025
Acceso en línea:Ver este registro en EBSCOhost
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        atl: Impact of a Genetic Diagnosis for a Child's Autism on Parental Perceptions.
      aug:
        au:
          Wynn, Julia
          Karlsen, Anna
          Huber, Benjamin
          Levine, Alina
          Salem, Amanie
          White, L. Casey
          Luby, Marti
          Bezborodko, Ekaterina
          Xiao, Sabrina
          Chung, Wendy K.
          Klitzman, Robert L.
          Appelbaum, Paul S.
        affil: https://ror.org/01esghr10 Department of Pediatrics, Columbia University Irving Medical Center, New York, NY, USA
      sug:
        subj:
          Autism Spectrum Disorder Diagnosis
          Autism Spectrum Disorder Familial and Genetic
          Autism Spectrum Disorder Psychosocial Factors
          Genetic Screening
          Parent-Child Relations
          Human
          Male
          Female
          Child, Preschool
          Child
          Adult
          Surveys
          Semi-Structured Interview
          Descriptive Statistics
          Sequence Analysis
          Multimethod Studies
          P-Value
          Comparative Studies
          Funding Source
          Child, Preschool: 2-5 years
          Child: 6-12 years
          Adult: 19-44 years
          Male
          Female
      ab: Genetic testing is recommended as part of an autism assessment, and most parents support genetic testing for their minor children. However, the impact on parents of receiving a monogenetic/ copy number variant diagnosis for autism in their child is not well understood. To explore this, we surveyed and interviewed parents of children in the SPARK study, a study of autism that includes genetic testing. Surveys were administered one month before and one and 12 months after parents received their child's genetic result. Interviews were conducted approximately one month after results disclosure. A genetic diagnosis (GD) for their child appeared to reduce parents' sense of self-blame and feelings of guilt, and this impact was relatively stable. The data also indicate a modest impact on parents' actions related to the condition, perceptions of themselves, and some aspects of life planning for their child, as measured by quantitative instruments at one month and 12 months after receipt of results. Other measures of parental identity and expectations for their child, in contrast, showed little change following receipt of genetic findings. Overall, parents who were told that no GD was identified showed minimal changes in their responses over time. These results suggest a discernable but relatively limited impact of genetic test results on parents of children with autism. These results should be reassuring to clinicians caring for children with autism and are consistent with studies in other areas of medicine that have suggested that genetic results tend to have fewer effects—negative or positive—than were anticipated.
      pubtype: Academic Journal
      doctype:
        research
        tables/charts
        Journal Article
      ougenre: Article
    language: English
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