Adolescents' and young adults' reactions to and perceived utility of carrier screening results in the context of a genomic research study.

Although guidelines have historically recommended deferring decisions about learning genomic information for conditions not actionable in childhood until adulthood, youth have increasing access to personal genomic information through research, clinical, and direct‐to‐consumer testing. However, littl...

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Published in:Journal of Genetic Counseling Vol. 34; no. 3; pp. 1 - 15
Main Authors: Grimes, Haley N., McGowan, Michelle L., Sinclair, Jessica A., Prows, Cynthia A., Lipstein, Ellen A., Myers, Melanie F.
Format: research tables/charts Journal Article
Published: Wiley-Blackwell Jun2025
Online Access:View this record in EBSCOhost
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      dt: Jun2025
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      pub: Wiley-Blackwell
      place: Malden, Massachusetts
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        atl: Adolescents' and young adults' reactions to and perceived utility of carrier screening results in the context of a genomic research study.
      aug:
        au:
          Grimes, Haley N.
          McGowan, Michelle L.
          Sinclair, Jessica A.
          Prows, Cynthia A.
          Lipstein, Ellen A.
          Myers, Melanie F.
        affil: Division of Human Genetics, Cincinnati Children's Hospital Medical Center, Cincinnati Ohio,, USA
      sug:
        subj:
          Genomics
          Genetics, Medical
          Genetic Research
          Genetic Screening In Adolescence
          Genetic Screening In Adulthood
          Decision Making In Adolescence
          Decision Making In Adulthood
          Genetic Privacy In Adolescence
          Genetic Privacy In Adulthood
          Human
          Male
          Female
          Adolescence
          Young Adult
          Qualitative Studies
          Semi-Structured Interview
          Coding
          Reproduction
          Age Factors
          Pedigree
          Funding Source
          Adolescent: 13-18 years
          Male
          Female
      ab: Although guidelines have historically recommended deferring decisions about learning genomic information for conditions not actionable in childhood until adulthood, youth have increasing access to personal genomic information through research, clinical, and direct‐to‐consumer testing. However, little is known about young people's reactions to, and perceived future utility of learning genomic information actionable in adulthood. We conducted qualitative interviews with 28 youth ages 15–22 without clinical indications for genetic screening who, through enrollment in a genomic decision‐making research study, learned they were carriers of an autosomal recessive condition, or anticipated being carriers but received negative results. Semi‐structured interviews occurred virtually between 3 and 16 months after the return of results. Interpretative description guided deductive and inductive coding of transcripts. Of the 28 participants, 21 received positive carrier results, and 7 received negative results. Although some carriers felt the result was unexpected, they expressed relief overall and did not feel worried about their result. Participants with negative results also felt relief about their results. All participants correctly described what a carrier result means, but some carriers could not remember the condition associated with their result. No participant regretted learning personal genomic information, and all reported their results helped them better understand risks to future children. Carriers who perceived the condition for which they were carriers as more severe and/or those familiar with the condition were more likely to remember their result and consider future reproductive options. Carriers also felt testing at their respective age allowed increased familiarity with results and more time to gather information and decide on the personal utility of the information. Our findings suggest early access to genomic information for some youth may allow integration of carrier information over time with minimal adverse effects. More research is needed to assess long‐term outcomes among carriers.
      pubtype: Academic Journal
      doctype:
        research
        tables/charts
        Journal Article
      ougenre: Article
    language: English
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