Aberrant brain structural-functional coupling and structural/functional network topology explain developmental delays in pediatric Prader-Willi syndrome.

Prader-Willi syndrome (PWS) is a neurodevelopmental disorder characterized by dysplasia in early life. Psychoradiology studies have suggested that mental and behavioral deficits in individuals with PWS are linked to abnormalities in brain structural and functional networks. However, little is known...

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Published in:European Child & Adolescent Psychiatry Vol. 34; no. 7; pp. 2155 - 2168
Main Authors: Huang, Zhongxin, Zheng, Helin, Wang, Longlun, Ding, Shuang, Li, Rong, Qing, Yong, Peng, Song, Zhu, Min, Cai, Jinhua
Format: diagnostic images research tables/charts Journal Article
Published: Springer Nature Jul2025
Online Access:View this record in EBSCOhost
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      dt: Jul2025
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      pub: Springer Nature
      place: New York, New York
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        10.1007/s00787-024-02631-3
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        atl: Aberrant brain structural-functional coupling and structural/functional network topology explain developmental delays in pediatric Prader-Willi syndrome.
      aug:
        au:
          Huang, Zhongxin
          Zheng, Helin
          Wang, Longlun
          Ding, Shuang
          Li, Rong
          Qing, Yong
          Peng, Song
          Zhu, Min
          Cai, Jinhua
        affil: https://ror.org/05pz4ws32 Department of Radiology, Women and Children's Hospital of Chongqing Medical University, 401147, Chongqing, China
      sug:
        subj:
          Prader-Willi Syndrome
          Brain Pathology
          Brain Physiopathology
          Functional Connectivity Evaluation
          Developmental Disabilities
          Magnetic Resonance Imaging
          Neuroradiography
          Human
          Funding Source
          Male
          Female
          Child
          Matched Case Control
          Large-Scale Brain Networks
          Neurodevelopment
          Child Development
          Child: 6-12 years
          Male
          Female
      ab: Prader-Willi syndrome (PWS) is a neurodevelopmental disorder characterized by dysplasia in early life. Psychoradiology studies have suggested that mental and behavioral deficits in individuals with PWS are linked to abnormalities in brain structural and functional networks. However, little is known about changes in network-based structural-functional coupling and structural/functional topological properties and their correlations with developmental scales in children with PWS. Here, we acquired diffusion tensor imaging and resting-state functional magnetic resonance imaging data from 25 children with PWS and 28 age- and sex-matched healthy controls, constructed structural and functional networks, examined intergroup differences in structural-functional coupling and structural/functional topological properties (both global and nodal), and tested their partial correlations with developmental scales. We found that children with PWS exhibited (1) decreased structural-functional coupling, (2) a higher characteristic path length and lower global efficiency in the structural network in terms of global properties, (3) alterations in classical cortical and subcortical networks in terms of nodal properties, with the structural network dominated by decreases and the functional network dominated by increases, and (4) partial correlation with developmental scales, especially for functional networks. These findings suggest that structural-functional decoupling and abundant structural/functional network topological properties may reveal the mechanism of early neurodevelopmental delays in PWS from a neuroimaging perspective and might serve as potential markers to assess early neurodevelopmental backwardness in PWS.
      pubtype: Academic Journal
      doctype:
        diagnostic images
        research
        tables/charts
        Journal Article
      ougenre: Article
    language: English
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