Analysis of the Alternative Splicing of an FGFR2 Transcript Due to a Novel 5′ Splice Site Mutation (1084++1G>A): Case Report.

Craniosynostosis is characterized by premature fusion of one or more cranial sutures and is associated with mutations in fibroblast growth factor receptor (FGFR) genes. Here we describe a novel mutation (1084++1G>A) in the FGFR2 gene of a patient with isolated bicoronal synostosis. We detected two i...

Descripción completa

Detalles Bibliográficos
Publicado en:Cleft Palate Craniofacial Journal Vol. 49; no. 1; pp. 104 - 109
Autores principales: Traynis, Ilana, Bernstein, Jonathan A, Gardner, Phyllis, Schrijver, Iris
Formato: case study diagnostic images tables/charts Journal Article
Publicado: Sage Publications Inc. Jan2012
Acceso en línea:Ver este registro en EBSCOhost
fields @attributes:
  recordID: 1
pdfLink:
plink: https://search.ebscohost.com/login.aspx?direct=true&db=ccm&AN=73568900&site=ehost-live
header:
  @attributes:
    shortDbName: ccm
    uiTerm: 73568900
    longDbName: CINAHL Complete
    uiTag: AN
  controlInfo:
    bkinfo:
    dissinfo:
    jinfo:
      jid:
        10556656
        DF1
      jtl: Cleft Palate Craniofacial Journal
      issn: 10556656
      maglogo: Y
    pubinfo:
      dt: Jan2012
      vid: 49
      iid: 1
      pid: 344
      pub: Sage Publications Inc.
      place: Thousand Oaks, California
    artinfo:
      ui:
        73568900
        104538549
        104538549
        10.1597/10-217
        73568900
      ppf: 104
      ppct: 5
      formats:
      tig:
        atl: Analysis of the Alternative Splicing of an FGFR2 Transcript Due to a Novel 5′ Splice Site Mutation (1084++1G>A): Case Report.
      aug:
        au:
          Traynis, Ilana
          Bernstein, Jonathan A
          Gardner, Phyllis
          Schrijver, Iris
      sug:
        subj:
          Craniosynostoses
          Mutation
          Male
          Child
          Tomography
          Polymerase Chain Reaction
          DNA Analysis
          Child: 6-12 years
          Male
      ab: Craniosynostosis is characterized by premature fusion of one or more cranial sutures and is associated with mutations in fibroblast growth factor receptor (FGFR) genes. Here we describe a novel mutation (1084++1G>A) in the FGFR2 gene of a patient with isolated bicoronal synostosis. We detected two isoforms that result from the mutation and are characterized, respectively, by exon skipping and the use of a cryptic splice site. Interestingly, the alternatively spliced forms of FGFR2 appear to induce fusion of the cranial sutures suggesting that the mutation acts via a gain-of-function mechanism rather than a loss of protein functionality.
      pubtype: Academic Journal
      doctype:
        case study
        diagnostic images
        tables/charts
        Journal Article
      ougenre: Article
    language: English
    refInfo:
    holdings:
      @attributes:
        islocal: N